An unusual case of unilateral vascular hypoplasia in an adult patient – late diagnosis of PHACE syndrome
A case of unilateral vascular hypoplasia is presented. A female patient was born with a complex aortic arch anatomy - a double aortic arch with an interrupted left arch. Surgical correction was performed at the age of 3 months. The patient was also noted to have had an ipsilateral large infantile ha...
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| Published in | International journal of cardiology congenital heart disease Vol. 13; p. 100465 |
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| Main Authors | , , , , , , , |
| Format | Journal Article |
| Language | English |
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Netherlands
Elsevier B.V
01.09.2023
Elsevier |
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| ISSN | 2666-6685 2666-6685 |
| DOI | 10.1016/j.ijcchd.2023.100465 |
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| Abstract | A case of unilateral vascular hypoplasia is presented. A female patient was born with a complex aortic arch anatomy - a double aortic arch with an interrupted left arch. Surgical correction was performed at the age of 3 months. The patient was also noted to have had an ipsilateral large infantile haemangioma. These findings raised the suspicion of the diagnosis of PHACE syndrome. PHACE syndrome is an acronym for Posterior fossa abnormalities, Haemangioma, Arterial anomalies, Cardiac anomalies and Eye anomalies. Future research is needed to elucidate the underlying pathophysiology in PHACE syndrome. |
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| AbstractList | A case of unilateral vascular hypoplasia is presented. A female patient was born with a complex aortic arch anatomy - a double aortic arch with an interrupted left arch. Surgical correction was performed at the age of 3 months. The patient was also noted to have had an ipsilateral large infantile haemangioma. These findings raised the suspicion of the diagnosis of PHACE syndrome. PHACE syndrome is an acronym for Posterior fossa abnormalities, Haemangioma, Arterial anomalies, Cardiac anomalies and Eye anomalies. Future research is needed to elucidate the underlying pathophysiology in PHACE syndrome.A case of unilateral vascular hypoplasia is presented. A female patient was born with a complex aortic arch anatomy - a double aortic arch with an interrupted left arch. Surgical correction was performed at the age of 3 months. The patient was also noted to have had an ipsilateral large infantile haemangioma. These findings raised the suspicion of the diagnosis of PHACE syndrome. PHACE syndrome is an acronym for Posterior fossa abnormalities, Haemangioma, Arterial anomalies, Cardiac anomalies and Eye anomalies. Future research is needed to elucidate the underlying pathophysiology in PHACE syndrome. A case of unilateral vascular hypoplasia is presented. A female patient was born with a complex aortic arch anatomy - a double aortic arch with an interrupted left arch. Surgical correction was performed at the age of 3 months. The patient was also noted to have had an ipsilateral large infantile haemangioma. These findings raised the suspicion of the diagnosis of PHACE syndrome. PHACE syndrome is an acronym for Posterior fossa abnormalities, Haemangioma, Arterial anomalies, Cardiac anomalies and Eye anomalies. Future research is needed to elucidate the underlying pathophysiology in PHACE syndrome. AbstractA case of unilateral vascular hypoplasia is presented. A female patient was born with a complex aortic arch anatomy - a double aortic arch with an interrupted left arch. Surgical correction was performed at the age of 3 months. The patient was also noted to have had an ipsilateral large infantile haemangioma. These findings raised the suspicion of the diagnosis of PHACE syndrome. PHACE syndrome is an acronym for Posterior fossa abnormalities, Haemangioma, Arterial anomalies, Cardiac anomalies and Eye anomalies. Future research is needed to elucidate the underlying pathophysiology in PHACE syndrome. |
| ArticleNumber | 100465 |
| Author | Lakeman, Inge M.M. Kiѐs, Philippine Stöger, J. Lauran Egorova, Anastasia D. Bökenkamp, Regina Jongbloed, Monique R.M. Hazekamp, Mark G. Regeer, Madelien V. |
| Author_xml | – sequence: 1 givenname: Madelien V. surname: Regeer fullname: Regeer, Madelien V. organization: CAHAL, Center for Congenital Heart Disease Amsterdam Leiden, Leiden University Medical Center, Leiden, the Netherlands – sequence: 2 givenname: J. Lauran surname: Stöger fullname: Stöger, J. Lauran organization: Department of Radiology, Leiden University Medical Center, Leiden, the Netherlands – sequence: 3 givenname: Regina surname: Bökenkamp fullname: Bökenkamp, Regina organization: CAHAL, Center for Congenital Heart Disease Amsterdam Leiden, Leiden University Medical Center, Leiden, the Netherlands – sequence: 4 givenname: Inge M.M. surname: Lakeman fullname: Lakeman, Inge M.M. organization: Department of Clinical Genetics, Leiden University Medical Center, Leiden, the Netherlands – sequence: 5 givenname: Mark G. surname: Hazekamp fullname: Hazekamp, Mark G. organization: CAHAL, Center for Congenital Heart Disease Amsterdam Leiden, Leiden University Medical Center, Leiden, the Netherlands – sequence: 6 givenname: Philippine surname: Kiѐs fullname: Kiѐs, Philippine organization: CAHAL, Center for Congenital Heart Disease Amsterdam Leiden, Leiden University Medical Center, Leiden, the Netherlands – sequence: 7 givenname: Anastasia D. surname: Egorova fullname: Egorova, Anastasia D. organization: CAHAL, Center for Congenital Heart Disease Amsterdam Leiden, Leiden University Medical Center, Leiden, the Netherlands – sequence: 8 givenname: Monique R.M. surname: Jongbloed fullname: Jongbloed, Monique R.M. email: m.r.m.jongbloed@lumc.nl organization: CAHAL, Center for Congenital Heart Disease Amsterdam Leiden, Leiden University Medical Center, Leiden, the Netherlands |
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| Keywords | Embryology Clinical genetics (Double) aortic arch Aberrant right subclavian artery Adult congenital heart disease PHACE syndrome Vascular hypoplasia |
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| References | Molin, Poelmann, DeRuiter, Azhar, Doetschman, Gittenberger-de Groot (bib11) 2004; 95 Molin, Roest, Nordstrand, Wisse, Poelmann, Eriksson, Gittenberger-De Groot (bib3) 2004; 70 Bayer, Frommelt, Blei, Jmpj, Cordisco, Frieden, Goddard, Holland, Krol, Maheshwari, Metry, Morel, North, Pope, Shieh, Southern, Wargon, Siegel, Drolet (bib9) 2013; 112 Frieden, Reese, Cohen (bib7) 1996; 132307–311 132 Metry, Garzon, Drolet, Frommelt, Haggstrom, Hall, Hess, Heyer, Siegel, Baselga, Katowitz, Levy, Mancini, Maronn, Phung, Pope, Sun, Frieden (bib10) 2009; 26 Hess, Fullerton, Metry, Drolet, Siegel, Auguste, Gupta, Haggstrom, Dowd, Frieden, Barkovich (bib8) 2010; 31 Li, Liu, Jin, Lu, Epstein (bib13) 1999; 126 Kau, Sinzig, Gasser, Lesnik, Rabitsch, Celedin, Eicher, Illiasch, Hausegger (bib5) 2007; 24 Tokuyama, Kiyosue, Baba, Asayama (bib1) 2021; 11 Garzon, Epstein, Heyer, Frommelt, Orbach, Baylis, Blei, Burrows, Chamlin, Chun, Hess, Joachim, Johnson, Kim, Liang, Maheshwari, McCoy, Metry, Monrad, Pope, Powell, Shwayder, Siegel, Tollefson, Vadivelu, Lew, Frieden, Drolet (bib6) 2016; 178 Martín-González, Díez-Solórzano, Blasco-Serra, Valverde-Navarro, Colás-López, Linuesa-Mendoza, Cortés-Aucejo, Ekuaga-Eyang, Jara-Jaquez, Cortés-Martínez (bib2) 2022; 44 Isselbacher, Preventza, Black, Augoustides, Beck, Bolen, Braverman, Bray, Brown-Zimmerman, Chen, Collins, DeAnda, Fanola, Girardi, Hicks, Hui, Schuyler Jones, Kalahasti, Kim, Milewicz, Oderich, Ogbechie, Promes, Ross, Schermerhorn, Singleton Times, Tseng, Wang, Woo (bib14) 2022; 80 van Rosendael, Stöger, Kiès, Vliegen, Hazekamp, Koolbergen, Lamb, Jongbloed, Egorova (bib4) 2021; 8 Tekgündüz, Ceviz, Kantarcı, Demirelli, Olgun, Caner, Şahin, Yolcu (bib12) 2014; 56 Martín-González (10.1016/j.ijcchd.2023.100465_bib2) 2022; 44 van Rosendael (10.1016/j.ijcchd.2023.100465_bib4) 2021; 8 Hess (10.1016/j.ijcchd.2023.100465_bib8) 2010; 31 Metry (10.1016/j.ijcchd.2023.100465_bib10) 2009; 26 Tekgündüz (10.1016/j.ijcchd.2023.100465_bib12) 2014; 56 Tokuyama (10.1016/j.ijcchd.2023.100465_bib1) 2021; 11 Li (10.1016/j.ijcchd.2023.100465_bib13) 1999; 126 Kau (10.1016/j.ijcchd.2023.100465_bib5) 2007; 24 Frieden (10.1016/j.ijcchd.2023.100465_bib7) 1996; 132307–311 132 Molin (10.1016/j.ijcchd.2023.100465_bib11) 2004; 95 Garzon (10.1016/j.ijcchd.2023.100465_bib6) 2016; 178 Molin (10.1016/j.ijcchd.2023.100465_bib3) 2004; 70 Isselbacher (10.1016/j.ijcchd.2023.100465_bib14) 2022; 80 Bayer (10.1016/j.ijcchd.2023.100465_bib9) 2013; 112 |
| References_xml | – volume: 132307–311 132 start-page: 307 year: 1996 end-page: 311 ident: bib7 article-title: PHACE syndrome. The association of posterior fossa brain malformations, hemangiomas, arterial anomalies, coarctation of the aorta and cardiac defects, and Eye abnormalities publication-title: Arch Dermatol – volume: 126 start-page: 2495 year: 1999 end-page: 2503 ident: bib13 article-title: Transgenic rescue of congenital heart disease and spina bifida in Splotch mice publication-title: Development – volume: 44 start-page: 531 year: 2022 end-page: 534 ident: bib2 article-title: Bilateral vertebral arteries arising distal to the left subclavian artery: embryological and anatomical description publication-title: Surg Radiol Anat – volume: 80 start-page: e223 year: 2022 end-page: e393 ident: bib14 article-title: ACC/AHA guideline for the diagnosis and management of aortic disease publication-title: J Am Coll Cardiol – volume: 70 start-page: 927 year: 2004 end-page: 938 ident: bib3 article-title: Disturbed morphogenesis of cardiac outflow tract and increased rate of aortic arch anomalies in the offspring of diabetic rats publication-title: Birth Defects Res A Clin Mol Teratol – volume: 24 start-page: 141 year: 2007 end-page: 152 ident: bib5 article-title: Aortic development and anomalies publication-title: Semin Intervent Radiol – volume: 56 start-page: 909 year: 2014 end-page: 910 ident: bib12 article-title: Rare cause of absence of femoral arterial pulse: bilateral common iliac artery hypoplasia publication-title: Pediatr Int – volume: 95 start-page: 1109 year: 2004 end-page: 1117 ident: bib11 article-title: Transforming growth factor β-SMAD2 signaling regulates aortic arch innervation and development publication-title: Circ Res – volume: 11 start-page: 8171 year: 2021 ident: bib1 article-title: Anomalous origin of the right vertebral artery publication-title: Appl Sci – volume: 178 start-page: 24 year: 2016 end-page: 33.e2 ident: bib6 article-title: PHACE syndrome: consensus-derived diagnosis and care recommendations publication-title: J Pediatr – volume: 112 start-page: 1948 year: 2013 end-page: 1952 ident: bib9 article-title: Congenital cardiac, aortic arch, and vascular bed anomalies in PHACE syndrome (from the International PHACE Syndrome Registry) publication-title: Am J Cardiol – volume: 26 start-page: 381 year: 2009 end-page: 398 ident: bib10 article-title: PHACE syndrome: current knowledge, future directions publication-title: Pediatr Dermatol – volume: 8 start-page: 1 year: 2021 end-page: 17 ident: bib4 article-title: The clinical spectrum of kommerell's diverticulum in adults with a right-sided aortic arch: a case series and literature overview publication-title: J Cardiovasc Dev Dis – volume: 31 start-page: 1980 year: 2010 end-page: 1986 ident: bib8 article-title: Cervical and intracranial arterial anomalies in 70 patients with PHACE syndrome publication-title: Am J Neuroradiol – volume: 132307–311 132 start-page: 307 year: 1996 ident: 10.1016/j.ijcchd.2023.100465_bib7 article-title: PHACE syndrome. The association of posterior fossa brain malformations, hemangiomas, arterial anomalies, coarctation of the aorta and cardiac defects, and Eye abnormalities publication-title: Arch Dermatol doi: 10.1001/archderm.1996.03890270083012 – volume: 44 start-page: 531 year: 2022 ident: 10.1016/j.ijcchd.2023.100465_bib2 article-title: Bilateral vertebral arteries arising distal to the left subclavian artery: embryological and anatomical description publication-title: Surg Radiol Anat doi: 10.1007/s00276-022-02903-0 – volume: 26 start-page: 381 year: 2009 ident: 10.1016/j.ijcchd.2023.100465_bib10 article-title: PHACE syndrome: current knowledge, future directions publication-title: Pediatr Dermatol doi: 10.1111/j.1525-1470.2009.00944.x – volume: 8 start-page: 1 year: 2021 ident: 10.1016/j.ijcchd.2023.100465_bib4 article-title: The clinical spectrum of kommerell's diverticulum in adults with a right-sided aortic arch: a case series and literature overview publication-title: J Cardiovasc Dev Dis – volume: 11 start-page: 8171 issue: 17 year: 2021 ident: 10.1016/j.ijcchd.2023.100465_bib1 article-title: Anomalous origin of the right vertebral artery publication-title: Appl Sci doi: 10.3390/app11178171 – volume: 56 start-page: 909 year: 2014 ident: 10.1016/j.ijcchd.2023.100465_bib12 article-title: Rare cause of absence of femoral arterial pulse: bilateral common iliac artery hypoplasia publication-title: Pediatr Int doi: 10.1111/ped.12343 – volume: 70 start-page: 927 year: 2004 ident: 10.1016/j.ijcchd.2023.100465_bib3 article-title: Disturbed morphogenesis of cardiac outflow tract and increased rate of aortic arch anomalies in the offspring of diabetic rats publication-title: Birth Defects Res A Clin Mol Teratol doi: 10.1002/bdra.20101 – volume: 126 start-page: 2495 year: 1999 ident: 10.1016/j.ijcchd.2023.100465_bib13 article-title: Transgenic rescue of congenital heart disease and spina bifida in Splotch mice publication-title: Development doi: 10.1242/dev.126.11.2495 – volume: 178 start-page: 24 year: 2016 ident: 10.1016/j.ijcchd.2023.100465_bib6 article-title: PHACE syndrome: consensus-derived diagnosis and care recommendations publication-title: J Pediatr doi: 10.1016/j.jpeds.2016.07.054 – volume: 24 start-page: 141 year: 2007 ident: 10.1016/j.ijcchd.2023.100465_bib5 article-title: Aortic development and anomalies publication-title: Semin Intervent Radiol doi: 10.1055/s-2007-980040 – volume: 95 start-page: 1109 year: 2004 ident: 10.1016/j.ijcchd.2023.100465_bib11 article-title: Transforming growth factor β-SMAD2 signaling regulates aortic arch innervation and development publication-title: Circ Res doi: 10.1161/01.RES.0000150047.16909.ab – volume: 112 start-page: 1948 year: 2013 ident: 10.1016/j.ijcchd.2023.100465_bib9 article-title: Congenital cardiac, aortic arch, and vascular bed anomalies in PHACE syndrome (from the International PHACE Syndrome Registry) publication-title: Am J Cardiol doi: 10.1016/j.amjcard.2013.08.025 – volume: 80 start-page: e223 issue: 24 year: 2022 ident: 10.1016/j.ijcchd.2023.100465_bib14 article-title: ACC/AHA guideline for the diagnosis and management of aortic disease publication-title: J Am Coll Cardiol doi: 10.1016/j.jacc.2022.08.004 – volume: 31 start-page: 1980 year: 2010 ident: 10.1016/j.ijcchd.2023.100465_bib8 article-title: Cervical and intracranial arterial anomalies in 70 patients with PHACE syndrome publication-title: Am J Neuroradiol doi: 10.3174/ajnr.A2206 |
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| SubjectTerms | (Double) aortic arch Aberrant right subclavian artery Adult congenital heart disease Cardiovascular Clinical genetics Embryology PHACE syndrome Vascular hypoplasia |
| Title | An unusual case of unilateral vascular hypoplasia in an adult patient – late diagnosis of PHACE syndrome |
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